Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Department of Internal Medicine, |
RCV000678041 | SCV000804195 | likely pathogenic | Heritable Thoracic Aortic Disease | 2018-04-01 | criteria provided, single submitter | research | This variant was identified in a family with thoracic aortic disease and no evidence of juvenile polyposis and/or hereditary hemorrhagic telangiectasia |
Labcorp Genetics |
RCV001304441 | SCV001493721 | uncertain significance | Juvenile polyposis syndrome | 2020-01-20 | criteria provided, single submitter | clinical testing | This variant has been observed in individual(s) with thoracic aortic aneurysm and dissection (PMID: 30809044). ClinVar contains an entry for this variant (Variation ID: 560163). This sequence change replaces arginine with leucine at codon 97 of the SMAD4 protein (p.Arg97Leu). The arginine residue is highly conserved and there is a moderate physicochemical difference between arginine and leucine. This variant is not present in population databases (ExAC no frequency). This variant has been reported to affect SMAD4 protein function (PMID: 30809044). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
University of Washington Center for Mendelian Genomics, |
RCV001261772 | SCV001439088 | likely pathogenic | Heritable thoracic aortic disease without juvenile polyposis and hereditary hemorrhagic telangiectasia | no assertion criteria provided | research |