Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000821148 | SCV000961892 | pathogenic | Primary immunodeficiency with post-measles-mumps-rubella vaccine viral infection | 2020-02-28 | criteria provided, single submitter | clinical testing | This sequence change affects a donor splice site in intron 13 of the STAT2 gene. It is expected to disrupt RNA splicing and likely results in an absent or disrupted protein product. For these reasons, this variant has been classified as Pathogenic. Donor and acceptor splice site variants typically lead to a loss of protein function (PMID: 16199547), and loss-of-function variants in STAT2 are known to be pathogenic (PMID: 23391734, 26122121). Experimental studies have shown that this variant disrupts mRNA splicing (Dr. Maciag, external communication). This variant has been observed in individual(s) with clinical features of STAT2 deficiency (Invitae). ClinVar contains an entry for this variant (Variation ID: 663294). This variant is not present in population databases (ExAC no frequency). |