Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002512863 | SCV003443214 | pathogenic | not provided | 2022-04-13 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Experimental studies have shown that this missense change affects NOG function (PMID: 17668388). Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive. ClinVar contains an entry for this variant (Variation ID: 6697). This missense change has been observed in individual(s) with NOG-related symphalangism spectrum disorder (PMID: 10080184, 11545688). In at least one individual the variant was observed to be de novo. It has also been observed to segregate with disease in related individuals. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces proline, which is neutral and non-polar, with arginine, which is basic and polar, at codon 35 of the NOG protein (p.Pro35Arg). |
Institute of Medical Genetics and Applied Genomics, |
RCV000049267 | SCV004100904 | pathogenic | Proximal symphalangism 1A | 2023-11-06 | criteria provided, single submitter | clinical testing | |
Juno Genomics, |
RCV000007085 | SCV005417020 | likely pathogenic | Tarsal-carpal coalition syndrome | criteria provided, single submitter | clinical testing | PM2_Supporting+PS3_Moderate+PS4_Supporting+PP1+PM6_Supporting+PP4 | |
OMIM | RCV000007085 | SCV000027281 | pathogenic | Tarsal-carpal coalition syndrome | 2001-09-01 | no assertion criteria provided | literature only | |
OMIM | RCV000049267 | SCV000077523 | pathogenic | Proximal symphalangism 1A | 2001-09-01 | no assertion criteria provided | literature only |