Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000057041 | SCV000321797 | pathogenic | not provided | 2015-12-14 | criteria provided, single submitter | clinical testing | The c.389_391delCCT pathogenic variant in the KRT16 gene results in an in-frame deletion of a single Serine residue. The deletion has been previously published in association with pachyonychia congenita type 1 (Smith et al., 1999). The variant was not observed in approximately 6,500 individuals of European and African American ancestry in the NHLBI Exome Sequencing Project, indicating it is not a common benign variant in these population. The deleted Serine residue is located at a position within the Coil1A region of the KRT16 protein that is a hotpot for pathogenic variants. |
OMIM | RCV000015707 | SCV000035972 | pathogenic | Pachyonychia congenita 1 | 1999-10-01 | no assertion criteria provided | literature only | |
Epithelial Biology; Institute of Medical Biology, |
RCV000057041 | SCV000088154 | not provided | not provided | no assertion provided | not provided |