Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Provincial Medical Genetics Program of British Columbia, |
RCV002211034 | SCV002496392 | likely pathogenic | Ataxia - intellectual disability - oculomotor apraxia - cerebellar cysts syndrome | 2022-01-01 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV002211034 | SCV005076780 | pathogenic | Ataxia - intellectual disability - oculomotor apraxia - cerebellar cysts syndrome | 2024-04-10 | criteria provided, single submitter | clinical testing | Variant summary: LAMA1 c.7009dupT (p.Ser2337PhefsX3) results in a premature termination codon, predicted to cause a truncation of the encoded protein or absence of the protein due to nonsense mediated decay, which are commonly known mechanisms for disease. The variant was absent in 251292 control chromosomes. To our knowledge, no occurrence of c.7009dupT in individuals affected with Ataxia-Intellectual Disability-Oculomotor Apraxia-Cerebellar Cysts Syndrome and no experimental evidence demonstrating its impact on protein function have been reported. ClinVar contains an entry for this variant (Variation ID: 1675305). Based on the evidence outlined above, the variant was classified as pathogenic. |