Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000687668 | SCV000815252 | uncertain significance | Congenital myasthenic syndrome 5 | 2022-08-31 | criteria provided, single submitter | clinical testing | This sequence change replaces isoleucine, which is neutral and non-polar, with methionine, which is neutral and non-polar, at codon 446 of the COLQ protein (p.Ile446Met). This variant is present in population databases (rs73818504, gnomAD 0.04%). This variant has not been reported in the literature in individuals affected with COLQ-related conditions. ClinVar contains an entry for this variant (Variation ID: 567550). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Not Available"; Align-GVGD: "Class C0"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Gene |
RCV001771938 | SCV001993475 | uncertain significance | not provided | 2019-08-20 | criteria provided, single submitter | clinical testing | In silico analysis, which includes protein predictors and evolutionary conservation, supports that this variant does not alter protein structure/function; Has not been previously published as pathogenic or benign to our knowledge |
Revvity Omics, |
RCV000687668 | SCV003829901 | uncertain significance | Congenital myasthenic syndrome 5 | 2023-08-09 | criteria provided, single submitter | clinical testing | |
Breakthrough Genomics, |
RCV001771938 | SCV005187541 | uncertain significance | not provided | criteria provided, single submitter | not provided | ||
Prevention |
RCV003907946 | SCV004718683 | likely benign | COLQ-related disorder | 2019-06-14 | no assertion criteria provided | clinical testing | This variant is classified as likely benign based on ACMG/AMP sequence variant interpretation guidelines (Richards et al. 2015 PMID: 25741868, with internal and published modifications). |