Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000810485 | SCV000950687 | pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency | 2024-01-25 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with histidine, which is basic and polar, at codon 377 of the MTHFR protein (p.Arg377His). This variant is present in population databases (rs750323424, gnomAD 0.004%). This missense change has been observed in individual(s) with methylenetetrahydrofolate reductase deficiency (PMID: 24797679, 25736335, 33089527). It has also been observed to segregate with disease in related individuals. ClinVar contains an entry for this variant (Variation ID: 654511). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) has been performed at Invitae for this missense variant, however the output from this modeling did not meet the statistical confidence thresholds required to predict the impact of this variant on MTHFR protein function. Experimental studies are conflicting or provide insufficient evidence to determine the effect of this variant on MTHFR function (PMID: 27743313). This variant disrupts the p.Arg377 amino acid residue in MTHFR. Other variant(s) that disrupt this residue have been observed in individuals with MTHFR-related conditions (PMID: 8940272, 12673793, 25736335, 26872964), which suggests that this may be a clinically significant amino acid residue. For these reasons, this variant has been classified as Pathogenic. |
Baylor Genetics | RCV003461196 | SCV004196398 | pathogenic | Neural tube defects, folate-sensitive | 2024-03-28 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV005012348 | SCV005634688 | likely pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency; Neural tube defects, folate-sensitive; Schizophrenia; Thrombophilia due to thrombin defect | 2024-04-04 | criteria provided, single submitter | clinical testing | |
Gene |
RCV005054269 | SCV005687924 | pathogenic | not provided | 2024-07-31 | criteria provided, single submitter | clinical testing | Published functional studies demonstrate a damaging effect (PMID: 27743313); Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 25736335, 26025547, 24797679, 34214447, 27743313, 33089527) |
Natera, |
RCV000810485 | SCV002094636 | likely pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency | 2021-04-26 | no assertion criteria provided | clinical testing |