Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000791536 | SCV000930791 | pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency | 2024-01-29 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Glu470*) in the MTHFR gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in MTHFR are known to be pathogenic (PMID: 25736335). This variant is present in population databases (no rsID available, gnomAD 0.003%). This premature translational stop signal has been observed in individuals with methylenetetrahydrofolate reductase deficiency (PMID: 25736335). ClinVar contains an entry for this variant (Variation ID: 638867). For these reasons, this variant has been classified as Pathogenic. |
Department of Medical Genetics, |
RCV000791536 | SCV001451948 | pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency | criteria provided, single submitter | research | ||
3billion | RCV000791536 | SCV003841510 | pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency | 2023-02-23 | criteria provided, single submitter | clinical testing | The variant is observed at an extremely low frequency in the gnomAD v2.1.1 dataset (total allele frequency: <0.001%). This variant was predicted to result in a loss or disruption of normal protein function through nonsense-mediated decay (NMD) or protein truncation. Multiple pathogenic variants are reported downstream of the variant. The variant has been reported at least twice as pathogenic with clinical assertions and evidence for the classification (ClinVar ID: VCV000638867). Therefore, this variant is classified as Pathogenic according to the recommendation of ACMG/AMP guideline. |
Baylor Genetics | RCV003461066 | SCV004196387 | pathogenic | Neural tube defects, folate-sensitive | 2024-01-25 | criteria provided, single submitter | clinical testing | |
Natera, |
RCV000791536 | SCV002094629 | pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency | 2021-05-05 | no assertion criteria provided | clinical testing |