Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001382824 | SCV001581759 | pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency | 2024-10-30 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with glutamine, which is neutral and polar, at codon 157 of the MTHFR protein (p.Arg157Gln). This variant is present in population databases (rs121434295, gnomAD 0.01%). This missense change has been observed in individual(s) with MTHFR deficiency (PMID: 7920641, 10679944, 25736335). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. It has also been observed to segregate with disease in related individuals. This variant is also known as 482G>A. ClinVar contains an entry for this variant (Variation ID: 3519). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is expected to disrupt MTHFR protein function with a positive predictive value of 95%. Experimental studies have shown that this missense change affects MTHFR function (PMID: 27743313). For these reasons, this variant has been classified as Pathogenic. |
Fulgent Genetics, |
RCV002476918 | SCV002801356 | likely pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency; Neural tube defects, folate-sensitive; Schizophrenia; Thrombophilia due to thrombin defect | 2021-12-28 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV003460410 | SCV004196396 | likely pathogenic | Neural tube defects, folate-sensitive | 2023-12-09 | criteria provided, single submitter | clinical testing | |
Gene |
RCV004719616 | SCV005325184 | pathogenic | not provided | 2024-01-09 | criteria provided, single submitter | clinical testing | Published functional studies found this variant is associated with significantly reduced MTHFR activity and reduced thermal stability compared to wild-type (PMID: 27743313); Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 31589614, 33574475, 29524840, 35008593, 36358396, 34214447, 7920641, 25736335, 33089527, 26872964, 31645654, 10679944, 27743313) |
OMIM | RCV001382824 | SCV000023859 | pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency | 1994-06-01 | no assertion criteria provided | literature only | |
Natera, |
RCV001382824 | SCV002094648 | pathogenic | Homocystinuria due to methylene tetrahydrofolate reductase deficiency | 2020-01-20 | no assertion criteria provided | clinical testing |