Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory for Molecular Medicine, |
RCV000614845 | SCV000731806 | uncertain significance | not specified | 2017-07-25 | criteria provided, single submitter | clinical testing | The p.Pro404Ala variant in WFS1 has not been previously reported in individuals with hearing loss or WFS1-related syndromes. It has been identified in 1/111718 European chromosomes by the Genome Aggregation Database (gnomAD, http://gnomad. broadinstitute.org; dbSNP rs756869880). Although this variant has been seen in t he general population, its frequency is not high enough to rule out a pathogenic role. Computational prediction tools and conservation analyses suggest that thi s variant may impact the protein, though this information is not predictive enou gh to determine pathogenicity. In summary, the clinical significance of this var iant is uncertain. |
Fulgent Genetics, |
RCV002498982 | SCV002806751 | uncertain significance | Cataract 41; Wolfram syndrome 1; Autosomal dominant nonsyndromic hearing loss 6; Type 2 diabetes mellitus; Wolfram-like syndrome | 2022-02-05 | criteria provided, single submitter | clinical testing | |
Clinical Genomics, |
RCV002509473 | SCV002817351 | uncertain risk allele | Wolfram syndrome 1 | criteria provided, single submitter | research | Potent mutations in WFS1 gene are associated with Wolfram's syndrome, an autosomal recessive condition, which cause diabetes mellitus, diabetes insipidus, deafness and optic atrophy.However no sufficient evidence is found to ascertain the role of this particular variant rs756869880 in Wolfram's syndrome yet. |