Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory for Molecular Medicine, |
RCV000614284 | SCV000712135 | uncertain significance | not specified | 2016-06-02 | criteria provided, single submitter | clinical testing | The p.Thr490Ala variant in WFS1 has not been previously reported in individuals with hearing loss or Wolfram syndrome, and it was absent from large population d atabases. Computational prediction tools and conservation analyses do not prov ide strong support for or against an impact to the protein. In summary, the clin ical significance of the p.Thr490Ala variant is uncertain. |
Clinical Genomics, |
RCV003126843 | SCV003801372 | likely benign | Wolfram syndrome 1 | criteria provided, single submitter | research | Potent mutations in WFS1 gene are associated with Wolfram's syndrome, an autosomal recessive condition, which cause diabetes mellitus, diabetes insipidus, deafness and optic atrophy. However no sufficient evidence is found to ascertain the role of this particular variant rs1553878548 in Wolfram's syndrome yet. |