Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000417564 | SCV000525414 | pathogenic | not provided | 2021-01-12 | criteria provided, single submitter | clinical testing | Not observed in large population cohorts (Lek et al., 2016); Missense variants in this gene are often considered pathogenic (Stenson et al., 2014); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 30744660, 29068161, 28250456) |
Institute of Human Genetics, |
RCV000767501 | SCV000898116 | likely pathogenic | Tubulinopathy | 2018-07-01 | criteria provided, single submitter | literature only | A variant that is classified as likely pathogenic has been identified in the TUBA1A gene in a born individual of unknown sex. The c.1246G>A, p.(Gly416Ser) variant has been reported as a variant of germline/unknown origin. |
Rady Children's Institute for Genomic Medicine, |
RCV001265592 | SCV001443757 | likely pathogenic | TUBA1A-associated tubulinopathy | 2019-12-06 | criteria provided, single submitter | clinical testing | The p.Gly416Ser variant has been reported in a large cohort study investigating the mutational and phenotypic spectrum of TUBA1A-associated tubulinopathy (PMID: 30744660). Additionally, the ClinVar database contains an entry for this variant (Variation ID: 384538). It is absent from the ExAC and gnomAD population databases and thus is presumed to be rare. The c.1246G>A (p.Gly416Ser) variant affects a highly conserved amino acid and is predicted by multiple in silico tools to have a deleterious effect on protein function. Analysis of the parental samples was negative for the variant, indicating this variant likely occurred as a de novo event. Based on the available evidence, the c.1246G>A (p.Gly416Ser) variant is classified as Likely Pathogenic. |