Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000759267 | SCV000543891 | pathogenic | not provided | 2023-11-22 | criteria provided, single submitter | clinical testing | This sequence change affects the initiator methionine of the POLE mRNA. The next in-frame methionine is located at codon 44. This variant is present in population databases (no rsID available, gnomAD 0.01%). Disruption of the initiator codon has been observed in individual(s) with clinical features of autosomal recessive FILS syndrome (PMID: 30503519). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. It has also been observed to segregate with disease in related individuals. ClinVar contains an entry for this variant (Variation ID: 405585). For these reasons, this variant has been classified as Pathogenic. |
Ambry Genetics | RCV000575992 | SCV000671649 | uncertain significance | Hereditary cancer-predisposing syndrome | 2018-10-03 | criteria provided, single submitter | clinical testing | The p.M1? variant (also known as c.1A>C), located in coding exon 1 of the POLE gene, results from an A to C substitution at nucleotide position 1. This alters the methionine residue at the initiation codon. However, there exists a possible alternate initiation site just 43 residues downstream. This amino acid position is well conserved on limited sequence alignment. Variations that modify the initiation codon (ATG) are expected to result in either loss of translation initiation or N-terminal truncation. However, as neither this specific alteration nor loss-of-function as a mechanism of pathogenicity have been well-described in the POLE gene, the clinical significance of this variant remains unknown. |
Gene |
RCV000759267 | SCV000680963 | uncertain significance | not provided | 2017-05-04 | criteria provided, single submitter | clinical testing | This variant alters the initiator Methionine codon, and the resultant protein would be described as“p.Met1?†to signify that it is not known if the loss of Met1 prevents all protein translation or if an abnormal protein isproduced using an alternate Methionine codon. POLE c.1A>C has not been previously published as a pathogenicvariant, nor has it been reported as a benign polymorphism to our knowledge. Based on currently available evidence,we consider it to be a variant of uncertain significance. |
Quest Diagnostics Nichols Institute San Juan Capistrano | RCV000759267 | SCV000888499 | uncertain significance | not provided | 2017-09-08 | criteria provided, single submitter | clinical testing | |
MGZ Medical Genetics Center | RCV000459323 | SCV002580547 | uncertain significance | Colorectal cancer, susceptibility to, 12 | 2021-12-20 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV002481391 | SCV002794322 | uncertain significance | Colorectal cancer, susceptibility to, 12; Facial dysmorphism-immunodeficiency-livedo-short stature syndrome; Intrauterine growth retardation, metaphyseal dysplasia, adrenal hypoplasia congenita, genital anomalies, and immunodeficiency | 2021-08-25 | criteria provided, single submitter | clinical testing |