Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003655124 | SCV000653491 | pathogenic | not provided | 2023-10-28 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Gln303*) in the POLE gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in POLE are known to be pathogenic (PMID: 23230001, 25948378, 30503519). This variant is present in population databases (rs749117997, gnomAD 0.01%). This variant has not been reported in the literature in individuals affected with POLE-related conditions. ClinVar contains an entry for this variant (Variation ID: 473841). For these reasons, this variant has been classified as Pathogenic. |
Ambry Genetics | RCV001018801 | SCV001180080 | uncertain significance | Hereditary cancer-predisposing syndrome | 2024-02-13 | criteria provided, single submitter | clinical testing | The p.Q303* variant (also known as c.907C>T), located in coding exon 9 of the POLE gene, results from a C to T substitution at nucleotide position 907. This changes the amino acid from a glutamine to a stop codon within coding exon 9. This alteration is expected to result in loss of function by premature protein truncation or nonsense-mediated mRNA decay. However, loss of function via haploinsufficiency in POLE has not been clearly established as a mechanism of disease. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |
Gene |
RCV003655124 | SCV005080458 | likely pathogenic | not provided | 2023-06-06 | criteria provided, single submitter | clinical testing | Nonsense variant predicted to result in protein truncation or nonsense mediated decay in a gene for which loss of function is a known mechanism of disease; Not observed at significant frequency in large population cohorts (gnomAD); Observed in an individual with endometrial cancer (Huang et al., 2018); This variant is associated with the following publications: (PMID: 29625052, 25948378, 23230001, 30503519) |
Fulgent Genetics, |
RCV005010520 | SCV005633766 | uncertain significance | Colorectal cancer, susceptibility to, 12; Facial dysmorphism-immunodeficiency-livedo-short stature syndrome; Intrauterine growth retardation, metaphyseal dysplasia, adrenal hypoplasia congenita, genital anomalies, and immunodeficiency | 2024-04-25 | criteria provided, single submitter | clinical testing |