Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics, |
RCV001095657 | SCV001251413 | likely pathogenic | Neurodevelopmental disorder with microcephaly, seizures, and cortical atrophy | 2019-10-01 | criteria provided, single submitter | clinical testing | The variant was confirmed as compound heterozygous with a variant of uncertain significance (NM_006295.2: c.1014G>T). |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV001095657 | SCV004122076 | pathogenic | Neurodevelopmental disorder with microcephaly, seizures, and cortical atrophy | 2023-10-24 | criteria provided, single submitter | clinical testing | Variant summary: VARS1 c.3622C>T (p.Arg1208X) results in a premature termination codon, predicted to cause absence of the protein due to nonsense mediated decay, which is a commonly known mechanism for disease. The variant allele was found at a frequency of 2.1e-05 in 243740 control chromosomes (gnomAD). c.3622C>T has been reported in the literature in an individual(s) affected with a Neurodevelopmental Disorder (Halfmeyer_2022). The following publication has been ascertained in the context of this evaluation (PMID: 36672771). One submitter has cited a clinical-significance assessment for this variant to ClinVar after 2014 and has classified the variant as likely pathogenic. Based on the evidence outlined above, the variant was classified as pathogenic. |