Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000032719 | SCV003250402 | uncertain significance | Craniolenticulosutural dysplasia | 2023-07-26 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Experimental studies have shown that this missense change affects SEC23A function (PMID: 22298774). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt SEC23A protein function. ClinVar contains an entry for this variant (Variation ID: 39521). This missense change has been observed in individual(s) with Craniolenticulosutural dysplasia (PMID: 21039434). This variant is present in population databases (rs138568622, gnomAD 0.06%), and has an allele count higher than expected for a pathogenic variant. This sequence change replaces methionine, which is neutral and non-polar, with valine, which is neutral and non-polar, at codon 702 of the SEC23A protein (p.Met702Val). |
OMIM | RCV000032719 | SCV000056483 | pathogenic | Craniolenticulosutural dysplasia | 2011-08-01 | no assertion criteria provided | literature only |