Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics Munich, |
RCV000995749 | SCV001150078 | likely pathogenic | Intellectual disability-feeding difficulties-developmental delay-microcephaly syndrome | 2019-06-11 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV001264541 | SCV001442746 | uncertain significance | not specified | 2020-10-02 | criteria provided, single submitter | clinical testing | Variant summary: CTCF c.1079G>T (p.Ser360Ile) results in a non-conservative amino acid change located in the Zinc finger C2H2-type domain (IPR013087) of the encoded protein sequence. Four of five in-silico tools predict a damaging effect of the variant on protein function. The variant was absent in 251476 control chromosomes. The available data on variant occurrences in the general population are insufficient to allow any conclusion about variant significance. To our knowledge, no occurrence of c.1079G>T in individuals affected with Mental retardation, autosomal dominant 21 and no experimental evidence demonstrating its impact on protein function have been reported in the literature. One ClinVar submitter (evaluation after 2014) cited the variant as Likely Pathogenic, reporting a de-novo occurrence in an individual affected with mental retardation, autosomal dominant 21, however no additional supporting evidence is provided. Based on the evidence outlined above, the variant was classified as uncertain significance. |