Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000087323 | SCV000941592 | pathogenic | Spastic ataxia 2 | 2022-11-24 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 101066). This premature translational stop signal has been observed in individuals with hereditary spastic paraplegia (PMID: 24319291, 24482476). It has also been observed to segregate with disease in related individuals. This variant is not present in population databases (gnomAD no frequency). This sequence change creates a premature translational stop signal (p.Arg731*) in the KIF1C gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in KIF1C are known to be pathogenic (PMID: 24319291, 24482476). |
OMIM | RCV000087323 | SCV000120203 | pathogenic | Spastic ataxia 2 | 2014-02-01 | no assertion criteria provided | literature only | |
Prevention |
RCV004752746 | SCV005342949 | pathogenic | KIF1C-related disorder | 2024-03-13 | no assertion criteria provided | clinical testing | The KIF1C c.2191C>T variant is predicted to result in premature protein termination (p.Arg731*). This variant in the homozygous condition was reported in two families with hereditary spastic paraplegia with cerebellar dysfunction (Dor et al. 2014. PubMed ID: 24319291; Family 803, Novarino et al. 2014. PubMed ID: 24482476). This variant has not been reported in a large population database, indicating this variant is rare. Nonsense variants in KIF1C are expected to be pathogenic. This variant is interpreted as pathogenic. |