Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001345964 | SCV001540119 | uncertain significance | Senior-Loken syndrome 7; Bardet-Biedl syndrome 16 | 2022-08-31 | criteria provided, single submitter | clinical testing | This sequence change replaces alanine, which is neutral and non-polar, with valine, which is neutral and non-polar, at codon 372 of the SDCCAG8 protein (p.Ala372Val). This variant is present in population databases (rs74701277, gnomAD 0.01%). This variant has not been reported in the literature in individuals affected with SDCCAG8-related conditions. ClinVar contains an entry for this variant (Variation ID: 1042069). Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be tolerated. Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may create or strengthen a splice site. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Fulgent Genetics, |
RCV001345964 | SCV002797594 | uncertain significance | Senior-Loken syndrome 7; Bardet-Biedl syndrome 16 | 2022-04-02 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV004531140 | SCV004733876 | uncertain significance | SDCCAG8-related disorder | 2023-11-22 | criteria provided, single submitter | clinical testing | The SDCCAG8 c.1115C>T variant is predicted to result in the amino acid substitution p.Ala372Val. To our knowledge, this variant has not been reported in the literature. This variant is reported in 0.011% of alleles in individuals of Latino descent in gnomAD. At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |