Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001992608 | SCV002224461 | uncertain significance | not provided | 2021-11-30 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C15"). This variant has not been reported in the literature in individuals affected with LZTR1-related conditions. The frequency data for this variant in the population databases is considered unreliable, as metrics indicate poor data quality at this position in the gnomAD database. This sequence change replaces arginine, which is basic and polar, with tryptophan, which is neutral and slightly polar, at codon 283 of the LZTR1 protein (p.Arg283Trp). |
Baylor Genetics | RCV003471098 | SCV004193606 | uncertain significance | Schwannomatosis 2 | 2023-07-26 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV004558754 | SCV005048050 | uncertain significance | Hereditary cancer-predisposing syndrome; Cardiovascular phenotype | 2023-10-06 | criteria provided, single submitter | clinical testing | The p.R283W variant (also known as c.847C>T), located in coding exon 9 of the LZTR1 gene, results from a C to T substitution at nucleotide position 847. The arginine at codon 283 is replaced by tryptophan, an amino acid with dissimilar properties. This amino acid position is highly conserved in available vertebrate species. In addition, this alteration is predicted to be deleterious by in silico analysis. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |