Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ambry Genetics | RCV002316836 | SCV000850604 | pathogenic | Inborn genetic diseases | 2017-04-20 | criteria provided, single submitter | clinical testing | The c.509+1G>A intronic pathogenic mutation results from a G to A substitution one nucleotide after coding exon 5 of the SYNGAP1 gene. This alteration was detected as de novo in an individual with moderate intellectual disability (ID) (Mignot C et al. J. Med. Genet., 2016 Aug;53:511-22). In addition to the clinical data presented in the literature, alterations that disrupt the canonical splice site are expected to cause aberrant splicing, resulting in an abnormal protein or a transcript that is subject to nonsense-mediated mRNA decay. As such, this alteration is classified as a disease-causing mutation. |
Gene |
RCV003442056 | SCV004169585 | pathogenic | not provided | 2023-05-18 | criteria provided, single submitter | clinical testing | Canonical splice site variant predicted to result in a null allele in a gene for which loss of function is a known mechanism of disease; Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 26989088, 30572772, 34924933) |