Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics, |
RCV001253809 | SCV004812077 | pathogenic | Optic atrophy 12 | 2024-04-05 | criteria provided, single submitter | clinical testing | Criteria applied: PS3,PS2_MOD,PS4_MOD,PM1,PM2_SUP,PP3 |
Unit of Genetics of Neurodegenerative and Metabolic Disease, |
RCV000684752 | SCV000803283 | pathogenic | Optic atrophy | 2018-08-06 | no assertion criteria provided | clinical testing | We report co-occurrence of a heterozygous de-novo AFG3L2 missense mutation (p.R468C) and a maternally-inherited heterozygous intragenic deletion of SPG7 in a patient with a complex ataxic and extrapyramidal phenotype with early-onset optic atrophy. Functional analysis in yeast model demonstrated that p.R468C abolished AFG3L2 function. |
OMIM | RCV001253809 | SCV001429682 | pathogenic | Optic atrophy 12 | 2020-08-14 | no assertion criteria provided | literature only |