Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Diagnostics Centre, |
RCV003445440 | SCV004174185 | likely pathogenic | Waardenburg syndrome type 4C | 2023-05-02 | no assertion criteria provided | clinical testing | The variant SOX10:c.512A>C, p.(Tyr171Ser), which is located in the coding exon 3 of the SOX10 gene, results from an adenine-to-cytosine substitution at nucleotide position 512. The tyrosine at protein position 171 is replaced by serine. SOX10 codes for the SRY-box transcription factor 10, and both loss-of-function variants and missense variants, particularly in the DNA-binding HMG-box, have been suggested to cause the associated syndromes. In silico analyses have assessed this alteration as severe (REVEL = 0.949). This variant can be classified as very rare in the overall population (no carriers in gnomAD). The variant is classified as Likely pathogenic. |