Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002040268 | SCV002301430 | likely pathogenic | not provided | 2024-12-08 | criteria provided, single submitter | clinical testing | This sequence change replaces proline, which is neutral and non-polar, with alanine, which is neutral and non-polar, at codon 190 of the SLC39A7 protein (p.Pro190Ala). This variant is present in population databases (rs563866464, gnomAD 0.007%). This missense change has been observed in individuals with agammaglobulinemia (PMID: 30718914). It has also been observed to segregate with disease in related individuals. ClinVar contains an entry for this variant (Variation ID: 1507871). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. Experimental studies have shown that this missense change affects SLC39A7 function (PMID: 30718914). In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. |
OMIM | RCV002271714 | SCV002056126 | pathogenic | Agammaglobulinemia 9, autosomal recessive | 2022-01-18 | no assertion criteria provided | literature only |