Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000488981 | SCV000576743 | uncertain significance | not provided | 2017-04-20 | criteria provided, single submitter | clinical testing | A variant of uncertain significance has been identified in the KCND2 gene. The c.821_825delACATT variant has not been published as a pathogenic variant, nor has it been reported as a benign variant to our knowledge. The c.821_825delACATT variant is not observed in large population cohorts (Lek et al., 2016; 1000 Genomes Consortium et al., 2015; Exome Variant Server). The c.821_825delACATT variant causes a frameshift starting with codon Tyrosine 274, changes this amino acid to a Tryptophan residue and creates a premature Stop codon at position 8 of the new reading frame, denoted p.Tyr274TrpfsX8. This variant is predicted to cause loss of normal protein function either through protein truncation or nonsense-mediated mRNA decay. Based on the currently available information, it is unclear whether this variant is a pathogenic variant or a rare benign variant. |
Labcorp Genetics |
RCV001856894 | SCV002165045 | uncertain significance | Early myoclonic encephalopathy | 2021-11-26 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. ClinVar contains an entry for this variant (Variation ID: 426332). This variant has not been reported in the literature in individuals affected with KCND2-related conditions. This variant is not present in population databases (gnomAD no frequency). This sequence change creates a premature translational stop signal (p.Tyr274Trpfs*8) in the KCND2 gene. It is expected to result in an absent or disrupted protein product. However, the current clinical and genetic evidence is not sufficient to establish whether loss-of-function variants in KCND2 cause disease. |