Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002539590 | SCV003439453 | likely pathogenic | Salla disease | 2023-04-19 | criteria provided, single submitter | clinical testing | This variant has not been reported in the literature in individuals affected with SLC17A5-related conditions. This variant is present in population databases (rs777862172, gnomAD 0.0009%). This sequence change affects a donor splice site in intron 8 of the SLC17A5 gene. It is expected to disrupt RNA splicing. Variants that disrupt the donor or acceptor splice site typically lead to a loss of protein function (PMID: 16199547), and loss-of-function variants in SLC17A5 are known to be pathogenic (PMID: 10581036, 10947946, 15172001). ClinVar contains an entry for this variant (Variation ID: 1252085). In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. |
Baylor Genetics | RCV002539590 | SCV004201238 | pathogenic | Salla disease | 2022-02-19 | criteria provided, single submitter | clinical testing | |
Center for Genomic Medicine, |
RCV001844399 | SCV001870522 | pathogenic | Sialic acid storage disease, severe infantile type | 2021-04-29 | no assertion criteria provided | research |