Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001065294 | SCV001230250 | uncertain significance | not provided | 2022-10-18 | criteria provided, single submitter | clinical testing | This sequence change replaces valine, which is neutral and non-polar, with alanine, which is neutral and non-polar, at codon 554 of the DHX38 protein (p.Val554Ala). This variant is present in population databases (rs374496350, gnomAD 0.02%). This missense change has been observed in individual(s) with clinical features of DHX38-related conditions (Invitae). ClinVar contains an entry for this variant (Variation ID: 859228). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt DHX38 protein function. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Dept Of Ophthalmology, |
RCV003890216 | SCV004706100 | uncertain significance | Retinal dystrophy | 2023-10-01 | criteria provided, single submitter | research |