Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Rady Children's Institute for Genomic Medicine, |
RCV000853242 | SCV000996058 | pathogenic | Insulin-dependent diabetes mellitus secretory diarrhea syndrome | 2017-02-27 | criteria provided, single submitter | clinical testing | The c.-23+1G>T is a canonical splice variant located between the untranslated exon 1 and intron 1 in the FOXP3 gene. It is predicted to result in aberrant splicing. This canonical splice site variant has been previously reported as pathogenic (PMID: 21802372) and a different variant at the same site (c.-23+1G>A) has also been reported as pathogenic (PMID: 25911531). Variants at this site result in the predicted disruption of the splice site at the exon 1/intron 1 junction. This deletion was not found in the 1000 Genomes, Exome Variant Server (EVS) or ExAC databases and is thus presumed to be rare. Based on the combined evidence, this variant is classified as pathogenic. |