Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000494097 | SCV000582594 | uncertain significance | not provided | 2017-05-16 | criteria provided, single submitter | clinical testing | The D3913H variant in the SACS gene has not been reported previously as a pathogenic variant, nor as a benign variant, to our knowledge. The D3913H variant is observed in 6/11570 (0.052%) alleles from individuals of Latino background, in the ExAC dataset (Lek et al., 2016). The D3913H variant is a non-conservative amino acid substitution, which is likely to impact secondary protein structure as these residues differ in polarity, charge, size and/or other properties. This substitution occurs at a position that is conserved in mammals. In silico analysis is inconsistent in its predictions as to whether or not the variant is damaging to the protein structure/function. We interpret D3913H as a variant of uncertain significance. |
Labcorp Genetics |
RCV002527093 | SCV003294901 | benign | Spastic paraplegia | 2023-07-17 | criteria provided, single submitter | clinical testing | |
Natera, |
RCV001829412 | SCV002086144 | uncertain significance | Charlevoix-Saguenay spastic ataxia | 2019-11-11 | no assertion criteria provided | clinical testing |