Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000691411 | SCV000819189 | pathogenic | Spastic paraplegia | 2023-05-12 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. This variant disrupts a region of the SACS protein in which other variant(s) (p.Arg3903*) have been determined to be pathogenic (PMID: 19892370, 21745802). This suggests that this is a clinically significant region of the protein, and that variants that disrupt it are likely to be disease-causing. ClinVar contains an entry for this variant (Variation ID: 549687). This premature translational stop signal has been observed in individual(s) with clinical features of SACS-related conditions (PMID: 29858556). This variant is not present in population databases (gnomAD no frequency). This sequence change creates a premature translational stop signal (p.Asp968Valfs*13) in the SACS gene. While this is not anticipated to result in nonsense mediated decay, it is expected to disrupt the last 3612 amino acid(s) of the SACS protein. |
Revvity Omics, |
RCV000664233 | SCV002019982 | pathogenic | Charlevoix-Saguenay spastic ataxia | 2021-01-08 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV000664233 | SCV004209954 | pathogenic | Charlevoix-Saguenay spastic ataxia | 2024-03-04 | criteria provided, single submitter | clinical testing | |
Mayo Clinic Laboratories, |
RCV004792355 | SCV005414140 | pathogenic | not provided | 2024-08-19 | criteria provided, single submitter | clinical testing | PM2, PM3_supporting, PVS1_strong |
Institute of Human Genetics, |
RCV000664233 | SCV000787799 | pathogenic | Charlevoix-Saguenay spastic ataxia | 2018-04-25 | no assertion criteria provided | clinical testing | |
Natera, |
RCV000664233 | SCV001453555 | pathogenic | Charlevoix-Saguenay spastic ataxia | 2020-09-16 | no assertion criteria provided | clinical testing |