Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Women's Health and Genetics/Laboratory Corporation of America, |
RCV002223097 | SCV002500828 | likely pathogenic | Joubert syndrome and related disorders | 2022-03-03 | criteria provided, single submitter | clinical testing | Variant summary: CEP104 c.1867_1870delTATG (p.Tyr623ArgfsX48) results in a premature termination codon, predicted to cause a truncation of the encoded protein or absence of the protein due to nonsense mediated decay, which are commonly known mechanisms for disease. The variant allele was found at a frequency of 4e-06 in 251436 control chromosomes (gnomAD). To our knowledge, no occurrence of c.1867_1870delTATG in individuals affected with Joubert Syndrome And Related Disorders and no experimental evidence demonstrating its impact on protein function have been reported. No clinical diagnostic laboratories have submitted clinical-significance assessments for this variant to ClinVar after 2014. Based on the evidence outlined above, the variant was classified as likely pathogenic. |