Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Molecular Genetics Laboratory, |
RCV004787558 | SCV005402670 | pathogenic | Neurodevelopmental disorder with speech impairment and dysmorphic facies | 2024-11-20 | criteria provided, single submitter | clinical testing | This variant was detected in a male with delayed speech and language development, global developmental delay, motor delay, Dandy-Walker malformation and obesity. The variant was confirmed to be of a de novo origin. Rare truncating variants affecting the SETD1A gene are well documented as a molecular cause of autosomal dominant "neurodevelopmental disorder with speech impairment and dysmorphic facies" (OMIM:619056) (PMID:32346159;26974950;25420024). To conclude, the variant is classified as pathogenic (ACMG PVS1, PM2, PS2). |