Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Lupski Lab, |
RCV000184017 | SCV000292313 | pathogenic | Charcot-Marie-Tooth disease, type 2A2A | 2015-09-17 | criteria provided, single submitter | research | This variant has been previously reported as disease-causing and was found in a 3.5 year old patient with peripheral neuropathy. |
Invitae | RCV001245336 | SCV001418618 | likely pathogenic | Charcot-Marie-Tooth disease, type 2 | 2019-10-10 | criteria provided, single submitter | clinical testing | This sequence change replaces serine with phenylalanine at codon 249 of the MFN2 protein (p.Ser249Phe). The serine residue is highly conserved and there is a large physicochemical difference between serine and phenylalanine. This variant is not present in population databases (ExAC no frequency). This variant has been observed in individuals with Charcot-Marie-Tooth disease (PMID: 21326314, 26378787, 26801520). In at least one individual the variant was observed to be de novo. ClinVar contains an entry for this variant (Variation ID: 202171). Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive, but these predictions have not been confirmed by published functional studies and their clinical significance is uncertain. In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. |
Mendelics | RCV000184017 | SCV000236548 | pathogenic | Charcot-Marie-Tooth disease, type 2A2A | 2013-02-14 | no assertion criteria provided | clinical testing | |
Inherited Neuropathy Consortium | RCV000789360 | SCV000928715 | uncertain significance | Charcot-Marie-Tooth disease | no assertion criteria provided | literature only |