Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Paris Brain Institute, |
RCV001391487 | SCV001450931 | pathogenic | Hereditary spastic paraplegia 4 | criteria provided, single submitter | clinical testing | ||
Labcorp Genetics |
RCV001391487 | SCV004292417 | pathogenic | Hereditary spastic paraplegia 4 | 2023-02-14 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Gln193*) in the SPAST gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in SPAST are known to be pathogenic (PMID: 20932283). For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 989092). This premature translational stop signal has been observed in individual(s) with hereditary spastic paraplegia (PMID: 10699187). This variant is not present in population databases (gnomAD no frequency). |