Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Paris Brain Institute, |
RCV001391489 | SCV001450933 | pathogenic | Hereditary spastic paraplegia 4 | criteria provided, single submitter | clinical testing | ||
Labcorp Genetics |
RCV001391489 | SCV005834304 | pathogenic | Hereditary spastic paraplegia 4 | 2024-07-16 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Tyr269*) in the SPAST gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in SPAST are known to be pathogenic (PMID: 20932283). This variant is not present in population databases (gnomAD no frequency). This premature translational stop signal has been observed in individual(s) with hereditary spastic paraplegia (PMID: 10699187, 18664244). ClinVar contains an entry for this variant (Variation ID: 989094). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. For these reasons, this variant has been classified as Pathogenic. |