Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001439470 | SCV001642356 | likely benign | Nephronophthisis 15 | 2024-12-02 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV001439470 | SCV002803394 | likely benign | Nephronophthisis 15 | 2021-11-11 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV005056662 | SCV005727038 | uncertain significance | not specified | 2024-11-06 | criteria provided, single submitter | clinical testing | Variant summary: CEP164 c.3610-4A>G alters a nucleotide located close to a canonical splice site and therefore could affect mRNA splicing, leading to a significantly altered protein sequence. Consensus agreement among computation tools predict no significant impact on normal splicing. However, these predictions have yet to be confirmed by functional studies. The variant allele was found at a frequency of 7.2e-05 in 1614066 control chromosomes, predominantly at a frequency of 0.0011 within the African or African-American subpopulation in the gnomAD database, including 1 homozygotes. This frequency is not significantly higher than estimated for a pathogenic variant in CEP164 causing Nephronophthisis 15, allowing no conclusion about variant significance. To our knowledge, no occurrence of c.3610-4A>G in individuals affected with Nephronophthisis 15 and no experimental evidence demonstrating its impact on protein function have been reported. ClinVar contains an entry for this variant (Variation ID: 720078). Based on the evidence outlined above, the variant was classified as VUS-possibly benign. |
Prevention |
RCV003957994 | SCV004782744 | likely benign | CEP164-related disorder | 2021-07-09 | no assertion criteria provided | clinical testing | This variant is classified as likely benign based on ACMG/AMP sequence variant interpretation guidelines (Richards et al. 2015 PMID: 25741868, with internal and published modifications). |