Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001039964 | SCV001203516 | uncertain significance | Nephronophthisis 15 | 2022-09-02 | criteria provided, single submitter | clinical testing | This variant, c.799_801del, results in the deletion of 1 amino acid(s) of the CEP164 protein (p.Lys267del), but otherwise preserves the integrity of the reading frame. This variant is present in population databases (rs764638875, gnomAD 0.06%). This variant has not been reported in the literature in individuals affected with CEP164-related conditions. ClinVar contains an entry for this variant (Variation ID: 838418). Experimental studies and prediction algorithms are not available or were not evaluated, and the functional significance of this variant is currently unknown. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Mayo Clinic Laboratories, |
RCV004792646 | SCV005412487 | uncertain significance | not provided | 2024-07-08 | criteria provided, single submitter | clinical testing | PM4 |
Fulgent Genetics, |
RCV001039964 | SCV005680748 | uncertain significance | Nephronophthisis 15 | 2024-06-05 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV004753168 | SCV005344545 | uncertain significance | CEP164-related disorder | 2024-07-22 | no assertion criteria provided | clinical testing | The CEP164 c.799_801delAAG variant is predicted to result in an in-frame deletion (p.Lys267del). To our knowledge, this variant has not been reported in the literature. This variant is reported in 0.058% of alleles in individuals of Latino descent in gnomAD, including one homozygote. Although we suspect that this variant may be benign, at this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |