Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clinical Genomics Laboratory, |
RCV004556029 | SCV005045189 | pathogenic | Microcephaly 18, primary, autosomal dominant | 2024-04-19 | criteria provided, single submitter | clinical testing | The WDFY3 c.7297_7298insC (p.Val2433Alafs*4) variant, to our knowledge, has not been reported in the medical literature and is absent from the general population (gnomAD v.2.1.1), indicating it is not a common variant. This variant causes a frameshift by inserting a single nucleotide, leading to a premature termination codon, which is predicted to lead to nonsense mediated decay. Furthermore, several loss of function variants downstream of this variant have been observed in affected individuals (Le Duc D et al., PMID: 31406988). Based on available information and the ACMG/AMP guidelines for variant interpretation (Richards S et al., PMID: 25741868), this variant is classified as pathogenic. |