Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000169359 | SCV000220730 | likely pathogenic | Megalencephalic leukoencephalopathy with subcortical cysts 1 | 2014-09-24 | criteria provided, single submitter | literature only | |
Labcorp Genetics |
RCV001850397 | SCV002239120 | pathogenic | not provided | 2024-12-02 | criteria provided, single submitter | clinical testing | This sequence change affects a donor splice site in intron 8 of the MLC1 gene. RNA analysis indicates that disruption of this splice site induces altered splicing and likely results in a shortened protein product. This variant is present in population databases (rs761620701, gnomAD 0.02%). Disruption of this splice site has been observed in individual(s) with megalencephalic leukoencephalopathy with subcortical cysts (PMID: 16652334). ClinVar contains an entry for this variant (Variation ID: 188980). Studies have shown that disruption of this splice site results in skipping of 9, but is expected to preserve the integrity of the reading-frame (PMID: 16652334). This variant disrupts a region of the MLC1 protein in which other variant(s) (p.Gly212Arg) have been determined to be pathogenic (PMID: 11254442, 21145992, 27322623). This suggests that this is a clinically significant region of the protein, and that variants that disrupt it are likely to be disease-causing. For these reasons, this variant has been classified as Pathogenic. |
Baylor Genetics | RCV000169359 | SCV004194993 | pathogenic | Megalencephalic leukoencephalopathy with subcortical cysts 1 | 2023-05-15 | criteria provided, single submitter | clinical testing |