Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001988800 | SCV002285355 | uncertain significance | not provided | 2023-12-27 | criteria provided, single submitter | clinical testing | This sequence change replaces asparagine, which is neutral and polar, with serine, which is neutral and polar, at codon 133 of the RHOBTB2 protein (p.Asn133Ser). This variant is present in population databases (rs766119429, gnomAD 0.002%). This variant has not been reported in the literature in individuals affected with RHOBTB2-related conditions. ClinVar contains an entry for this variant (Variation ID: 1491653). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt RHOBTB2 protein function with a negative predictive value of 80%. Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may create or strengthen a splice site. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Revvity Omics, |
RCV003138014 | SCV003816146 | uncertain significance | Developmental and epileptic encephalopathy, 64 | 2020-07-08 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV003289358 | SCV003961300 | uncertain significance | Inborn genetic diseases | 2023-06-13 | criteria provided, single submitter | clinical testing | The c.398A>G (p.N133S) alteration is located in exon 6 (coding exon 4) of the RHOBTB2 gene. This alteration results from a A to G substitution at nucleotide position 398, causing the asparagine (N) at amino acid position 133 to be replaced by a serine (S). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |