Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001226277 | SCV001398585 | uncertain significance | Familial aplasia of the vermis; Meckel-Gruber syndrome | 2022-08-31 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with glutamine, which is neutral and polar, at codon 355 of the RPGRIP1L protein (p.Arg355Gln). The frequency data for this variant in the population databases is considered unreliable, as metrics indicate poor data quality at this position in the gnomAD database. This variant has not been reported in the literature in individuals affected with RPGRIP1L-related conditions. ClinVar contains an entry for this variant (Variation ID: 953913). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Tolerated"; PolyPhen-2: "Possibly Damaging"; Align-GVGD: "Class C0"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Fulgent Genetics, |
RCV002484229 | SCV002778714 | uncertain significance | Joubert syndrome 7; Meckel syndrome, type 5; COACH syndrome 3 | 2021-10-13 | criteria provided, single submitter | clinical testing | |
Natera, |
RCV001828807 | SCV002085743 | uncertain significance | Familial aplasia of the vermis | 2020-07-22 | no assertion criteria provided | clinical testing | |
Prevention |
RCV004733191 | SCV005347701 | uncertain significance | RPGRIP1L-related disorder | 2024-07-03 | no assertion criteria provided | clinical testing | The RPGRIP1L c.1064G>A variant is predicted to result in the amino acid substitution p.Arg355Gln. To our knowledge, this variant has not been reported in the literature. This variant is reported in 0.0029% of alleles in individuals of Latino descent in gnomAD. At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |