Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Genetic Services Laboratory, |
RCV001816689 | SCV002067483 | likely pathogenic | not provided | 2020-04-13 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001816689 | SCV002978509 | pathogenic | not provided | 2022-11-21 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt VPS13D protein function. ClinVar contains an entry for this variant (Variation ID: 561198). This missense change has been observed in individual(s) with VPS13D-related conditions (PMID: 29604224). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. It has also been observed to segregate with disease in related individuals. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces glycine, which is neutral and non-polar, with aspartic acid, which is acidic and polar, at codon 1190 of the VPS13D protein (p.Gly1190Asp). |
OMIM | RCV000680228 | SCV000807682 | pathogenic | Autosomal recessive cerebellar ataxia-saccadic intrusion syndrome | 2018-09-14 | no assertion criteria provided | literature only |