Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000128425 | SCV001586052 | pathogenic | Tumor predisposition syndrome 3 | 2023-05-13 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Experimental studies have shown that this missense change affects POT1 function (PMID: 24686846, 27869160). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt POT1 protein function. ClinVar contains an entry for this variant (Variation ID: 139525). This missense change has been observed in individual(s) with melanoma (PMID: 24686846). It has also been observed to segregate with disease in related individuals. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces serine, which is neutral and polar, with asparagine, which is neutral and polar, at codon 270 of the POT1 protein (p.Ser270Asn). |
Sema4, |
RCV002256085 | SCV002527176 | pathogenic | Hereditary cancer-predisposing syndrome | 2021-10-14 | criteria provided, single submitter | curation | |
Ambry Genetics | RCV002256085 | SCV002679115 | uncertain significance | Hereditary cancer-predisposing syndrome | 2024-06-19 | criteria provided, single submitter | clinical testing | The p.S270N variant (also known as c.809G>A), located in coding exon 6 of the POT1 gene, results from a G to A substitution at nucleotide position 809. The serine at codon 270 is replaced by asparagine, an amino acid with highly similar properties. This variant was identified in 1/167 Italian individuals with cutaneous melanoma who were CDKN2A/ARF- and CDK4-negative (Pastorino L et al. Cancers (Basel), 2020 04;12:). This variant was also identified in five unrelated melanoma-prone families from Romagna, Italy and described as a founder mutation (Shi J et al. Nat Genet, 2014 May;46:482-6). This amino acid position is not well conserved in available vertebrate species. In addition, this alteration is predicted to be tolerated by in silico analysis. Based on the available evidence, the clinical significance of this variant remains unclear. |
OMIM | RCV000128425 | SCV000172103 | pathogenic | Tumor predisposition syndrome 3 | 2014-05-01 | no assertion criteria provided | literature only | |
Gene |
RCV000128425 | SCV001478028 | not provided | Tumor predisposition syndrome 3 | no assertion provided | literature only | Founder variant in Romagna region of Italy |