Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Foundation for Research in Genetics and Endocrinology, |
RCV002467479 | SCV002762848 | pathogenic | Autism spectrum disorder due to AUTS2 deficiency | 2021-09-01 | criteria provided, single submitter | research | A heterozygous missense variation in exon 9 of the AUTS2 gene that results in the amino acid substitution of Arginine for Glycine at codon 511 was detected. The observed variant c.1531G>A (p.Gly511Arg) has not been reported in the 1000 genomes and gnomAD databases. The in silico prediction of the variant are probably damaging by PolyPhen-2 (HumDiv) and damaging by SIFT, LRT and MutationTaster2. The reference codon is conserved across species. Segregation analysis showed the variant to be de novo. In summary, the variant meets our criteria to be classified as pathogenic. |
Gene |
RCV003222432 | SCV003918344 | uncertain significance | not provided | 2022-10-14 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; Has not been previously published as pathogenic or benign to our knowledge |