Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics, |
RCV002468883 | SCV002765095 | likely pathogenic | Joubert syndrome 18 | 2022-12-02 | criteria provided, single submitter | clinical testing | Criteria applied: PVS1,PM2_SUP; Identified as compund heterozygous with NM_015631.6:c.566A>G |
Labcorp Genetics |
RCV002571430 | SCV003023844 | pathogenic | Orofacial-digital syndrome IV; Joubert syndrome 18 | 2023-09-13 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 1804145). Disruption of the initiator codon has been observed in individual(s) with Joubert syndrome (PMID: 26092869; Invitae). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. This variant is not present in population databases (gnomAD no frequency). This sequence change affects the initiator methionine of the TCTN3 mRNA. The next in-frame methionine is located at codon 152. |