Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
DBGen Ocular Genomics | RCV001591793 | SCV001815890 | uncertain significance | Retinitis pigmentosa 71 | 2021-06-16 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV002506690 | SCV002815332 | uncertain significance | Short-rib thoracic dysplasia 10 with or without polydactyly; Retinitis pigmentosa 71; Bardet-Biedl syndrome 20 | 2024-02-16 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV002571156 | SCV003254333 | uncertain significance | Short-rib thoracic dysplasia 10 with or without polydactyly; Retinitis pigmentosa 71 | 2022-07-24 | criteria provided, single submitter | clinical testing | This sequence change replaces threonine, which is neutral and polar, with methionine, which is neutral and non-polar, at codon 329 of the IFT172 protein (p.Thr329Met). This variant is present in population databases (rs568736482, gnomAD 0.06%). This variant has not been reported in the literature in individuals affected with IFT172-related conditions. ClinVar contains an entry for this variant (Variation ID: 1213851). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
SN ONGC Dept of Genetics and Molecular biology Vision Research Foundation | RCV003224574 | SCV003920709 | likely pathogenic | Bardet-Biedl syndrome | criteria provided, single submitter | research | ||
Breakthrough Genomics, |
RCV004692703 | SCV005187525 | uncertain significance | not provided | criteria provided, single submitter | not provided | ||
Prevention |
RCV004551934 | SCV004745588 | uncertain significance | IFT172-related disorder | 2023-12-05 | no assertion criteria provided | clinical testing | The IFT172 c.986C>T variant is predicted to result in the amino acid substitution p.Thr329Met. To our knowledge, this variant has not been reported in the literature. This variant has been documented in 0.056% of alleles in individuals of South Asian descent in gnomAD, which is likely too common for an undocumented disease-causing variant. Although we suspect that this variant may be benign, at this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |