Total submissions: 7
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV001558258 | SCV001780167 | pathogenic | not provided | 2024-08-26 | criteria provided, single submitter | clinical testing | Observed with a second SBDS variant in two other unrelated families in published literature (PMID: 15701631); Frameshift variant predicted to result in protein truncation or nonsense mediated decay in a gene for which loss-of-function is a known mechanism of disease; Not observed at a significant frequency in large population cohorts (gnomAD); Also known as c.292_295delAAAG; This variant is associated with the following publications: (PMID: 15701631, 15942154) |
Fulgent Genetics, |
RCV002482895 | SCV002792939 | pathogenic | Shwachman-Diamond syndrome 1; Aplastic anemia | 2022-04-22 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV003473117 | SCV004202352 | pathogenic | Aplastic anemia | 2022-07-07 | criteria provided, single submitter | clinical testing | |
Gene |
RCV000020729 | SCV000041304 | not provided | Shwachman-Diamond syndrome 1 | no assertion provided | literature only | ||
Joint Genome Diagnostic Labs from Nijmegen and Maastricht, |
RCV001558258 | SCV001957628 | pathogenic | not provided | no assertion criteria provided | clinical testing | ||
Clinical Genetics DNA and cytogenetics Diagnostics Lab, |
RCV001558258 | SCV001973563 | pathogenic | not provided | no assertion criteria provided | clinical testing | ||
Prevention |
RCV003904855 | SCV004721628 | pathogenic | SBDS-related disorder | 2024-01-24 | no assertion criteria provided | clinical testing | The SBDS c.297_300delAAGA variant is predicted to result in a frameshift and premature protein termination (p.Glu99Aspfs*21). This variant has been reported to be causative for Shwachman-Diamond Syndrome (Shammas et al. 2005. PubMed ID: 15701631, reported as 292_295delAAAG). This variant is reported in 0.0040% of alleles in individuals of African descent in gnomAD. Frameshift variants in SBDS are expected to be pathogenic. This variant is interpreted as pathogenic. |