Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
ARUP Laboratories, |
RCV000756403 | SCV000884205 | uncertain significance | Autosomal recessive nonsyndromic hearing loss 3 | 2018-10-15 | criteria provided, single submitter | clinical testing | The p.Cys2184Arg variant has not been reported in the medical literature, is not listed in gene-specific variant databases, nor has it been previously identified in our laboratory. It is also absent from population databases such as 1000 Genomes, the NHLBI GO Exome Sequencing Project (ESP), and the Genome Aggregation Database (gnomAD) browser. The cysteine at codon 2184 is highly conserved considering 11 species up to Cow (Alamut software v2.9), and computational analyses suggest this variant has a significant effect on MYO15A protein structure/function (SIFT: damaging, PolyPhen2: damaging, and Mutation Taster: disease causing). However, based on the available information, the clinical significance of the p.Cys2184Arg variant cannot be determined with certainty. |