Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Prevention |
RCV003415655 | SCV004109317 | pathogenic | RAB23-related disorder | 2023-06-12 | criteria provided, single submitter | clinical testing | The RAB23 c.408dupT variant is predicted to result in premature protein termination (p.Glu137*). This variant was reported in the homozygous state in two apparently unrelated individual with carpenter syndrome (Jenkins et al 2007. PubMed ID: 17503333). This variant has not been reported in a large population database (http://gnomad.broadinstitute.org), indicating it is rare. Nonsense variants in RAB23 are expected to be pathogenic. This variant is interpreted as pathogenic. |
Gene |
RCV004721242 | SCV005327164 | pathogenic | not provided | 2023-07-01 | criteria provided, single submitter | clinical testing | Nonsense variant predicted to result in protein truncation or nonsense mediated decay in a gene for which loss of function is a known mechanism of disease; Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 17503333) |
OMIM | RCV000004854 | SCV000025030 | pathogenic | RAB23-related Carpenter syndrome | 2007-06-01 | no assertion criteria provided | literature only |