Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Illumina Laboratory Services, |
RCV000004366 | SCV000914981 | uncertain significance | Deficiency of beta-ureidopropionase | 2018-11-26 | criteria provided, single submitter | clinical testing | The UPB1 c.209G>C (p.Arg70Pro) missense variant has been reported in a compound heterozygous state in one individual with multiple congenital anomalies and beta-ureidopropionase deficiency (Yaplito-Lee et al. 2008). Control data are unavailable for this variant, which is reported at a frequency of 0.000349 in the European American population of the Exome Sequencing Project. Yaplito-Lee et al. (2008) performed functional analysis of the p.Arg70Pro variant by expressing the variant in E. coli and found that no beta-ureidopropionase activity was detected. Based on the evidence, the p.Arg70Pro variant is classified as a variant of unknown significance but suspicious for pathogenicity for beta-ureidopropionase deficiency. This variant was observed by ICSL as part of a predisposition screen in an ostensibly healthy population. |
Baylor Genetics | RCV000004366 | SCV001527898 | uncertain significance | Deficiency of beta-ureidopropionase | 2018-03-12 | criteria provided, single submitter | clinical testing | This variant was determined to be of uncertain significance according to ACMG Guidelines, 2015 [PMID:25741868]. |
OMIM | RCV000004366 | SCV000024537 | pathogenic | Deficiency of beta-ureidopropionase | 2008-02-01 | no assertion criteria provided | literature only |